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Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour

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Resumo:The carcinoid syndrome is rare but it is associated with carcinoid heart disease in more than a half of the cases. Carcinoid heart disease is typically characterised by morphological and functional modifications of right-sided valves. Its aetiology is probable multifactorial but serotonin appears to play a key role in the development of this valvular disease. Unlike gastrointestinal neuroendocrine tumours, ovarian neuroendocrine tumours can present with carcinoid syndrome and carcinoid heart disease in the absence of liver metastases; such ovarian neuroendocrine tumours are a unique clinical entity. The additional burden of cardiac impairment in these patients represents a significant reduction in survival. Early recognition and surgical valve replacement before advanced heart failure is established may improve the clinical outcome. We report the case of a woman with an ovarian neuroendocrine tumour and highly symptomatic carcinoid heart disease who was submitted to tumour resection followed by valvuloplasty. She demonstrated an outstanding clinical improvement and has remained free of tumour and symptomatology.
Autores principais:Simões-Pereira, Joana
Outros Autores:Wang, Lai Mun; Kardos, Attila; Grossman, Ashley
Assunto:Carcinoma Neuroendocrine Carcinoid Heart Disease Carcinoid Tumor Ovarian Neoplasms Carcinoma Neuroendócrino Doença Carcinoide Cardíaca Neoplasias do Ovário Tumor Carcinoide
Ano:2017
País:Portugal
Tipo de documento:artigo
Tipo de acesso:unknown
Instituição associada:Ordem dos Médicos
Idioma:inglês
Origem:Acta Médica Portuguesa
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author Simões-Pereira, Joana
author2 Wang, Lai Mun
Kardos, Attila
Grossman, Ashley
author2_role author
author
author
author_facet Simões-Pereira, Joana
Simões-Pereira, Joana
Wang, Lai Mun
Kardos, Attila
Grossman, Ashley
Wang, Lai Mun
Kardos, Attila
Grossman, Ashley
author_role author
country_str PT
creators_json_str [{\"Person.name\":\"Simões-Pereira, Joana\"},{\"Person.name\":\"Wang, Lai Mun\"},{\"Person.name\":\"Kardos, Attila\"},{\"Person.name\":\"Grossman, Ashley\"}]
datacite.creators.creator.creatorName.fl_str_mv Simões-Pereira, Joana
Wang, Lai Mun
Kardos, Attila
Grossman, Ashley
datacite.rights.fl_str_mv http://purl.org/coar/access_right/c_abf2
datacite.subjects.subject.fl_str_mv Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
datacite.titles.title.fl_str_mv Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
Síndrome Carcinoide e Doença Carcinoide Cardíaca como Manifestações de Tumor Neuroendócrino do Ovário Não Metastático
dc.creator.none.fl_str_mv Simões-Pereira, Joana
Wang, Lai Mun
Kardos, Attila
Grossman, Ashley
dc.description.none.fl_str_mv A síndrome carcinoide é rara mas encontra-se associada, em cerca de metade dos casos, a doença carcinoide cardíaca. Esta patologia cardíaca caracteriza-se tipicamente por alterações morfo-funcionais das válvulas direitas. A sua etiologia é provavelmente multifatorial mas, aparentemente, a serotonina parece exercer um papel preponderante no desenvolvimento desta doença valvular. Ao contrário dos tumores neuroendócrinos gastrointestinais, os tumores neuroendócrinos do ovário podem apresentar síndrome carcinoide e doença carcinoide cardíaca na ausência de metastização hepática, tornando os tumores neuroendócrinos do ovário uma entidade clínica única. Estas alterações cardíacas acarretam uma diminuição adicional da sobrevivência destes doentes. Portanto, o reconhecimento precoce desta entidade e a substituição valvular prévia ao estabelecimento da insuficiência cardíaca avançada podem melhorar a evolução clínica destes doentes. Os autores apresentam o caso de uma mulher com tumor neuroendócrino do ovário e doença carcinoide cardíaca muito sintomática que foi submetida a resseção tumoral seguida de valvuloplastia. A doente demonstrou uma marcada melhoria clínica e tem permanecido livre de doença e assintomática.
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dc.identifier.none.fl_str_mv https://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713
dc.language.none.fl_str_mv eng
dc.publisher.none.fl_str_mv Ordem dos Médicos
dc.rights.none.fl_str_mv http://purl.org/coar/access_right/c_abf2
dc.source.none.fl_str_mv Acta Médica Portuguesa; Vol. 30 No. 5 (2017): May; 421-425
Acta Médica Portuguesa; Vol. 30 N.º 5 (2017): Maio; 421-425
1646-0758
0870-399X
dc.subject.none.fl_str_mv Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
dc.title.fl_str_mv Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
Síndrome Carcinoide e Doença Carcinoide Cardíaca como Manifestações de Tumor Neuroendócrino do Ovário Não Metastático
dc.type.none.fl_str_mv http://purl.org/coar/resource_type/c_6501
description The carcinoid syndrome is rare but it is associated with carcinoid heart disease in more than a half of the cases. Carcinoid heart disease is typically characterised by morphological and functional modifications of right-sided valves. Its aetiology is probable multifactorial but serotonin appears to play a key role in the development of this valvular disease. Unlike gastrointestinal neuroendocrine tumours, ovarian neuroendocrine tumours can present with carcinoid syndrome and carcinoid heart disease in the absence of liver metastases; such ovarian neuroendocrine tumours are a unique clinical entity. The additional burden of cardiac impairment in these patients represents a significant reduction in survival. Early recognition and surgical valve replacement before advanced heart failure is established may improve the clinical outcome. We report the case of a woman with an ovarian neuroendocrine tumour and highly symptomatic carcinoid heart disease who was submitted to tumour resection followed by valvuloplasty. She demonstrated an outstanding clinical improvement and has remained free of tumour and symptomatology.
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person_str_mv Simões-Pereira, Joana
Wang, Lai Mun
Kardos, Attila
Grossman, Ashley
publishDate 2017
publisher.none.fl_str_mv Ordem dos Médicos
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spelling en-USCarcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumourpt-PTSíndrome Carcinoide e Doença Carcinoide Cardíaca como Manifestações de Tumor Neuroendócrino do Ovário Não MetastáticoSimões-Pereira, JoanaWang, Lai MunKardos, AttilaGrossman, AshleyCarcinomaNeuroendocrineCarcinoid Heart DiseaseCarcinoid TumorOvarian NeoplasmsCarcinoma NeuroendócrinoDoença Carcinoide CardíacaNeoplasias do OvárioTumor CarcinoideDireitos de Autor (c) 2017 Acta Médica Portuguesahttp://purl.org/coar/access_right/c_abf2https://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713URLhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/5051URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8421URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8422URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8736URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8737URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8738URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8739URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8740URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8864URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8865URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8866URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8867URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8868URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8869URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8914URLHasVersionhttps://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713/8915URLHasVersion2017-05-31en-USThe carcinoid syndrome is rare but it is associated with carcinoid heart disease in more than a half of the cases. Carcinoid heart disease is typically characterised by morphological and functional modifications of right-sided valves. Its aetiology is probable multifactorial but serotonin appears to play a key role in the development of this valvular disease. Unlike gastrointestinal neuroendocrine tumours, ovarian neuroendocrine tumours can present with carcinoid syndrome and carcinoid heart disease in the absence of liver metastases; such ovarian neuroendocrine tumours are a unique clinical entity. The additional burden of cardiac impairment in these patients represents a significant reduction in survival. Early recognition and surgical valve replacement before advanced heart failure is established may improve the clinical outcome. We report the case of a woman with an ovarian neuroendocrine tumour and highly symptomatic carcinoid heart disease who was submitted to tumour resection followed by valvuloplasty. She demonstrated an outstanding clinical improvement and has remained free of tumour and symptomatology.pt-PTA síndrome carcinoide é rara mas encontra-se associada, em cerca de metade dos casos, a doença carcinoide cardíaca. Esta patologia cardíaca caracteriza-se tipicamente por alterações morfo-funcionais das válvulas direitas. A sua etiologia é provavelmente multifatorial mas, aparentemente, a serotonina parece exercer um papel preponderante no desenvolvimento desta doença valvular. Ao contrário dos tumores neuroendócrinos gastrointestinais, os tumores neuroendócrinos do ovário podem apresentar síndrome carcinoide e doença carcinoide cardíaca na ausência de metastização hepática, tornando os tumores neuroendócrinos do ovário uma entidade clínica única. Estas alterações cardíacas acarretam uma diminuição adicional da sobrevivência destes doentes. Portanto, o reconhecimento precoce desta entidade e a substituição valvular prévia ao estabelecimento da insuficiência cardíaca avançada podem melhorar a evolução clínica destes doentes. Os autores apresentam o caso de uma mulher com tumor neuroendócrino do ovário e doença carcinoide cardíaca muito sintomática que foi submetida a resseção tumoral seguida de valvuloplastia. A doente demonstrou uma marcada melhoria clínica e tem permanecido livre de doença e assintomática.Ordem dos Médicosapplication/pdfimage/jpegapplication/mswordimage/jpegimage/jpegimage/jpegimage/jpegapplication/mswordapplication/mswordimage/tiffimage/tiffimage/jpegimage/jpegimage/jpegapplication/pdfapplication/pdfen-USActa Médica Portuguesa; Vol. 30 No. 5 (2017): May; 421-425pt-PTActa Médica Portuguesa; Vol. 30 N.º 5 (2017): Maio; 421-4251646-07580870-399Xengjournal articlehttp://purl.org/coar/resource_type/c_6501literatureVoRhttp://purl.org/coar/version/c_970fb48d4fbd8a85
spellingShingle Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
Simões-Pereira, Joana
Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
Simões-Pereira, Joana
Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
status NEW
status_str VoR
subject.fl_str_mv Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
title Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
title_full Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
title_fullStr Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
title_full_unstemmed Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
title_short Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
title_sort Carcinoid Syndrome and Carcinoid Heart Disease as Manifestations of Non-Metastatic Ovarian Neuroendocrine Tumour
topic Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
topic_facet Carcinoma
Neuroendocrine
Carcinoid Heart Disease
Carcinoid Tumor
Ovarian Neoplasms
Carcinoma Neuroendócrino
Doença Carcinoide Cardíaca
Neoplasias do Ovário
Tumor Carcinoide
url https://www.actamedicaportuguesa.com/revista/index.php/amp/article/view/7713
visible 1