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Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration

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Resumo:Age-related macular degeneration (AMD) is the leading cause of vision loss in the Western world, and it currently lacks effective therapy. It is believed that AMD initiates in the aged retinal pigment epithelium (RPE), which presents lysosomal dysfunction and oxidative stress (OxS) that ultimately leads to RPE damage and AMD progression. AMD is a complex pathology, so multitarget treatments are required to act on different pathways, presenting several challenges. In this review, we discuss the current knowledge on the pathogenesis of this disease, focusing mainly on lysosomal dysfunction and OxS. Because transcription factors regulate homeostasis, the transcription factor EB (TFEB), which controls lysosomal function and biogenesis, and the nuclear factor erythroid 2-related factor 2 (NRF2), which manages OxS, have been proposed as promising targets for disease intervention. Finally, we discuss the interplay of these pathways for a potential synergistic effect on AMD-targeted therapies, as they could change the course of today’s available treatments for AMD.
Autores principais:Falcão, Ana S.
Outros Autores:AS, Falcão; Pedro, Margarida L.; Tenreiro, Sandra; Tenreiro, Sandra; Seabra, Miguel C.; C Seabra, Miguel
Assunto:age-related macular degeneration lysosomal dysfunction NRF2 oxidative stress retinal pigment epithelium TFEB/mTORC1 axis Food Science Physiology Biochemistry Molecular Biology Clinical Biochemistry Cell Biology
Ano:2025
País:Portugal
Tipo de documento:recensão
Tipo de acesso:acesso aberto
Instituição associada:Universidade Nova de Lisboa
Idioma:inglês
Origem:Repositório Institucional da UNL
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author Falcão, Ana S.
author2 AS, Falcão
Pedro, Margarida L.
Tenreiro, Sandra
Tenreiro, Sandra
Seabra, Miguel C.
C Seabra, Miguel
author2_role author
author
author
author
author
author
author_facet Falcão, Ana S.
AS, Falcão
Pedro, Margarida L.
Tenreiro, Sandra
Tenreiro, Sandra
Seabra, Miguel C.
C Seabra, Miguel
author_role author
contributor_name_str_mv iNOVA4Health - pólo NMS
NOVA Medical School|Faculdade de Ciências Médicas (NMS|FCM)
MDPI - Multidisciplinary Digital Publishing Institute
RUN
country_str PT
creators_json_txt [{\"Person.name\":\"Falcão, Ana S.\"},{\"Person.name\":\"AS, Falcão\",\"Person.identifier.orcid\":\"0000-0002-4491-7457\"},{\"Person.name\":\"Pedro, Margarida L.\"},{\"Person.name\":\"Tenreiro, Sandra\"},{\"Person.name\":\"Tenreiro, Sandra\",\"Person.identifier.orcid\":\"0000-0001-7272-5842\"},{\"Person.name\":\"Seabra, Miguel C.\"},{\"Person.name\":\"C Seabra, Miguel\",\"Person.identifier.orcid\":\"0000-0002-6404-4892\"}]
datacite.contributors.contributor.contributorName.fl_str_mv iNOVA4Health - pólo NMS
NOVA Medical School|Faculdade de Ciências Médicas (NMS|FCM)
MDPI - Multidisciplinary Digital Publishing Institute
RUN
datacite.creators.creator.creatorName.fl_str_mv Falcão, Ana S.
AS, Falcão
Pedro, Margarida L.
Tenreiro, Sandra
Tenreiro, Sandra
Seabra, Miguel C.
C Seabra, Miguel
datacite.date.Accepted.fl_str_mv 2025-05-01T00:00:00Z
datacite.date.available.fl_str_mv 2025-07-01T21:17:46Z
datacite.date.embargoed.fl_str_mv 2025-07-01T21:17:46Z
datacite.rights.fl_str_mv http://purl.org/coar/access_right/c_abf2
datacite.subjects.subject.fl_str_mv age-related macular degeneration
lysosomal dysfunction
NRF2
oxidative stress
retinal pigment epithelium
TFEB/mTORC1 axis
Food Science
Physiology
Biochemistry
Molecular Biology
Clinical Biochemistry
Cell Biology
datacite.titles.title.fl_str_mv Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
dc.contributor.none.fl_str_mv iNOVA4Health - pólo NMS
NOVA Medical School|Faculdade de Ciências Médicas (NMS|FCM)
MDPI - Multidisciplinary Digital Publishing Institute
RUN
dc.creator.none.fl_str_mv Falcão, Ana S.
AS, Falcão
Pedro, Margarida L.
Tenreiro, Sandra
Tenreiro, Sandra
Seabra, Miguel C.
C Seabra, Miguel
dc.date.Accepted.fl_str_mv 2025-05-01T00:00:00Z
dc.date.available.fl_str_mv 2025-07-01T21:17:46Z
dc.date.embargoed.fl_str_mv 2025-07-01T21:17:46Z
dc.format.none.fl_str_mv application/pdf
dc.identifier.none.fl_str_mv http://hdl.handle.net/10362/184706
dc.language.none.fl_str_mv eng
dc.rights.none.fl_str_mv http://purl.org/coar/access_right/c_abf2
dc.subject.none.fl_str_mv age-related macular degeneration
lysosomal dysfunction
NRF2
oxidative stress
retinal pigment epithelium
TFEB/mTORC1 axis
Food Science
Physiology
Biochemistry
Molecular Biology
Clinical Biochemistry
Cell Biology
dc.title.fl_str_mv Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
dc.type.none.fl_str_mv http://purl.org/coar/resource_type/c_efa0
description Age-related macular degeneration (AMD) is the leading cause of vision loss in the Western world, and it currently lacks effective therapy. It is believed that AMD initiates in the aged retinal pigment epithelium (RPE), which presents lysosomal dysfunction and oxidative stress (OxS) that ultimately leads to RPE damage and AMD progression. AMD is a complex pathology, so multitarget treatments are required to act on different pathways, presenting several challenges. In this review, we discuss the current knowledge on the pathogenesis of this disease, focusing mainly on lysosomal dysfunction and OxS. Because transcription factors regulate homeostasis, the transcription factor EB (TFEB), which controls lysosomal function and biogenesis, and the nuclear factor erythroid 2-related factor 2 (NRF2), which manages OxS, have been proposed as promising targets for disease intervention. Finally, we discuss the interplay of these pathways for a potential synergistic effect on AMD-targeted therapies, as they could change the course of today’s available treatments for AMD.
dirty 0
eu_rights_str_mv openAccess
format review
fulltext.url.fl_str_mv https://run.unl.pt/bitstreams/fd5005ad-6735-45c5-a33d-f8c7475c0383/download
id run_198f719f94deae86b4951549c8484911
identifier.url.fl_str_mv http://hdl.handle.net/10362/184706
inst_facet_str urn:organizationAcronym:unl{{{_:::_}}}Universidade Nova de Lisboa
instacron_str unl
institution Universidade Nova de Lisboa
instname_str Universidade Nova de Lisboa
language eng
network_acronym_str run
network_name_str Repositório Institucional da UNL
oai_identifier_str oai:run.unl.pt:10362/184706
organization_str_mv urn:organizationAcronym:unl
person_str_mv Falcão, Ana S.
AS, Falcão
AS, Falcão
https://www.ciencia-id.pt/EC17-1F25-9969
EC17-1F25-9969
http://orcid.org/0000-0002-4491-7457
0000-0002-4491-7457
Pedro, Margarida L.
Tenreiro, Sandra
Tenreiro, Sandra
Tenreiro, Sandra
https://www.ciencia-id.pt/2214-5455-2764
2214-5455-2764
http://orcid.org/0000-0001-7272-5842
0000-0001-7272-5842
Seabra, Miguel C.
C Seabra, Miguel
C Seabra, Miguel
https://www.ciencia-id.pt/2512-FAEF-E26F
2512-FAEF-E26F
http://orcid.org/0000-0002-6404-4892
0000-0002-6404-4892
publishDate 2025
repo_facet_str urn:repositoryAcronym:run{{{_:::_}}}Repositório Institucional da UNL
reponame_str Repositório Institucional da UNL
repository_id_str urn:repositoryAcronym:run
service_str_mv urn:repositoryAcronym:run
spelling engenAge-related macular degeneration (AMD) is the leading cause of vision loss in the Western world, and it currently lacks effective therapy. It is believed that AMD initiates in the aged retinal pigment epithelium (RPE), which presents lysosomal dysfunction and oxidative stress (OxS) that ultimately leads to RPE damage and AMD progression. AMD is a complex pathology, so multitarget treatments are required to act on different pathways, presenting several challenges. In this review, we discuss the current knowledge on the pathogenesis of this disease, focusing mainly on lysosomal dysfunction and OxS. Because transcription factors regulate homeostasis, the transcription factor EB (TFEB), which controls lysosomal function and biogenesis, and the nuclear factor erythroid 2-related factor 2 (NRF2), which manages OxS, have been proposed as promising targets for disease intervention. Finally, we discuss the interplay of these pathways for a potential synergistic effect on AMD-targeted therapies, as they could change the course of today’s available treatments for AMD.application/pdfenTargeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular DegenerationFalcão, Ana S.PersonalAS, FalcãoDSpacehttp://dspace.org/items/7baf07a3-9ea7-4765-bf51-88caf9163a5cDSpacehttp://dspace.org/items/7baf07a3-9ea7-4765-bf51-88caf9163a5cFalcãoAnaCiência IDhttps://www.ciencia-id.ptEC17-1F25-9969ORCIDhttp://orcid.org0000-0002-4491-7457Researcher IDhttps://www.researcherid.comM-5600-2013Scopus Author IDhttps://www.scopus.com8896201400Pedro, Margarida L.Tenreiro, SandraPersonalTenreiro, SandraDSpacehttp://dspace.org/items/69a3db58-3303-47a3-a7bb-b19d9ba8c36aDSpacehttp://dspace.org/items/69a3db58-3303-47a3-a7bb-b19d9ba8c36aTenreiroSandraCiência IDhttps://www.ciencia-id.pt2214-5455-2764ORCIDhttp://orcid.org0000-0001-7272-5842Researcher IDhttps://www.researcherid.comA-9289-2013Scopus Author IDhttps://www.scopus.com6602925840Seabra, Miguel C.PersonalC Seabra, MiguelDSpacehttp://dspace.org/items/d6eeb095-df2d-4fd0-8241-ab826e5ecb1dDSpacehttp://dspace.org/items/d6eeb095-df2d-4fd0-8241-ab826e5ecb1dSeabraMiguelCiência IDhttps://www.ciencia-id.pt2512-FAEF-E26FORCIDhttp://orcid.org0000-0002-6404-4892Researcher IDhttps://www.researcherid.comM-3280-2013Scopus Author IDhttps://www.scopus.com7004369652iNOVA4Health - pólo NMSNOVA Medical School|Faculdade de Ciências Médicas (NMS|FCM)MDPI - Multidisciplinary Digital Publishing InstituteHostingInstitutionOrganizationalRUNe-mailmailto:run@unl.ptrun@unl.ptISSNIsPartOf2076-3921URNIsPartOfPURE: 118628312URNIsPartOfPURE UUID: cb901666-2d72-4d18-a843-7f2cf711616bURNIsPartOfScopus: 105007651012DOIIsPartOf10.3390/antiox140505962025-07-01T21:17:46Z2025-052025-05-01T00:00:00ZHandlehttp://hdl.handle.net/10362/184706http://purl.org/coar/access_right/c_abf2open accessage-related macular degenerationlysosomal dysfunctionNRF2oxidative stressretinal pigment epitheliumTFEB/mTORC1 axisFood SciencePhysiologyBiochemistryMolecular BiologyClinical BiochemistryCell Biology2078779 bytesother research producthttp://purl.org/coar/resource_type/c_efa0reviewhttp://purl.org/coar/access_right/c_abf2application/pdffulltexthttps://run.unl.pt/bitstreams/fd5005ad-6735-45c5-a33d-f8c7475c0383/download
spellingShingle Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
Falcão, Ana S.
age-related macular degeneration
lysosomal dysfunction
NRF2
oxidative stress
retinal pigment epithelium
TFEB/mTORC1 axis
Food Science
Physiology
Biochemistry
Molecular Biology
Clinical Biochemistry
Cell Biology
status SINGLETON
subject.fl_str_mv age-related macular degeneration
lysosomal dysfunction
NRF2
oxidative stress
retinal pigment epithelium
TFEB/mTORC1 axis
Food Science
Physiology
Biochemistry
Molecular Biology
Clinical Biochemistry
Cell Biology
title Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
title_full Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
title_fullStr Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
title_full_unstemmed Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
title_short Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
title_sort Targeting Lysosomal Dysfunction and Oxidative Stress in Age-Related Macular Degeneration
topic age-related macular degeneration
lysosomal dysfunction
NRF2
oxidative stress
retinal pigment epithelium
TFEB/mTORC1 axis
Food Science
Physiology
Biochemistry
Molecular Biology
Clinical Biochemistry
Cell Biology
topic_facet age-related macular degeneration
lysosomal dysfunction
NRF2
oxidative stress
retinal pigment epithelium
TFEB/mTORC1 axis
Food Science
Physiology
Biochemistry
Molecular Biology
Clinical Biochemistry
Cell Biology
url http://hdl.handle.net/10362/184706
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