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Distal renal tubular acidosis and sensorineural deafness with mutation in the ATP6V1B1 gene

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Detalhes bibliográficos
Resumo:Distal renal tubular acidosis is a rare disorder characterized by the inability in acidification of urine, conditioning hyperchloraemic acidosis, hypokalaemia, hypercalciuria and nephrocalcinosis, which can cause growth retardation, abnormal bone metabolism and, when untreated, chronic renal failure. Distal renal tubular acidosis and sensorineural deafness is an autosomal recessive disease caused by mutations in the gene encoding B1 subunit of H+ -ATPase (ATP6V1B1). The authors report the cases of two sisters who presented failure to thrive, changes in ionic and acid-base balance and sensorineural deafness. A homozygous mutation in ATP6V1B1 gene was detected in both girls. These two cases are intended to highlight the importance of an early diagnosis in this rare disease
Autores principais:Periquito,Isabel
Outros Autores:Casimiro,Anaxore; Santo,Catarina E.; D’Elia,Cláudio; Abranches,Margarida; Castro,Isabel
Assunto:Distal renal tubular acidosis sensorineural deafness
Ano:2013
País:Portugal
Tipo de documento:artigo
Tipo de acesso:acesso aberto
Instituição associada:Fundação para a Ciência e Tecnologia
Idioma:inglês
Origem:SciELO Portugal
Descrição
Resumo:Distal renal tubular acidosis is a rare disorder characterized by the inability in acidification of urine, conditioning hyperchloraemic acidosis, hypokalaemia, hypercalciuria and nephrocalcinosis, which can cause growth retardation, abnormal bone metabolism and, when untreated, chronic renal failure. Distal renal tubular acidosis and sensorineural deafness is an autosomal recessive disease caused by mutations in the gene encoding B1 subunit of H+ -ATPase (ATP6V1B1). The authors report the cases of two sisters who presented failure to thrive, changes in ionic and acid-base balance and sensorineural deafness. A homozygous mutation in ATP6V1B1 gene was detected in both girls. These two cases are intended to highlight the importance of an early diagnosis in this rare disease